Original scientific article
Tracheal bifurcation located at proximal third of oesophageal length
in Sprague Dawley rats of all ages
by Andreas Lindnera, Evangelos Tagkalosb, Axel Heimannc, Maximilian Nuberd, Jan Baumgartd, Nadine Baumgartd, Oliver J. Muensterera, Christina Oetzmann von Sochaczewskia
aDepartment of Paediatric Surgery, Universitätsmedizin Mainz der
Johannes-Gutenberg-Universität
bDepartment of General, Visceral and Transplant Surgery,
Universitätsmedizin Mainz der Johannes-Gutenberg-Universität
cInstitute of Neurosurgical Pathophysiology, Universitätsmedizin Mainz
der Johannes-Gutenberg-Universität
dTranslational Animal Research Centre, Johannes-Gutenberg-Universität
Mainz
ORCiDs: A.H.: https://orcid.org/0000-0003-2510-3228;
J.B.: https://orcid.org/0000-0003-1996-4267;
N.B.: https://orcid.org/0000-0002-6684-0198;
O.J.M.: https://orcid.org/0000-0003-2790-4395;
C.O.: https://orcid.org/0000-0002-3469-777X.
Correspondence: Christina Oetzmann von
Sochaczewski
Klinik und Poliklinik für Kinderchirurgie, Universitätsmedizin Mainz,
Langenbeckstraße 1, D-55131 Mainz, Germany
Phone: +49 6131 17 2056
Fax: +49 6131 17 6523
E-mail: c.oetzmann@gmail.com
Summary
Levrat’s rat model is often the first choice for basic studies
of oesophageal adenocarcinoma. The position of the tracheal
bifurcation represents the preferred location for the
high-intrathoracic anastomosis following oesophagectomy for cancer and
is thus of importance in basic research of oesophageal adenocarcinoma.
In addition, it is also the typical location for trachea-oesophageal
fistulae in congenital oesophageal atresia and its rat model. We thus
analysed whether the position of the tracheal bifurcation would be
affected by a rat’s growth throughout life. We analysed absolute
and relative carinal position of the tracheal bifurcation and its
relationship to oesophageal length in two cohorts of Sprague Dawley
rats (RjHan:SD) of both sexes: one consisted of 30 eight-week old rats
and the other of 20 rats aged between 15 and 444 days. We analysed
their relationship by Pearson’s r and univariate linear
regression. Bootstrap confidence intervals were calculated for all
calculated coefficients. Absolute carinal position correlated with
oesophageal length in the eight-week old cohort (r=0.4, 95%
CI: 0.08-0.71, p=0.015) and those of different ages
(r=0.92, 95% CI: 0.77-0.96, p=0.0066). Absolute
carinal position increased with oesophageal length in both cohorts
(F(1,28)=5.56; p=0.0256 and F(1,18)=94.93; p<0.0001 respectively).
Consequently, relative tracheal bifurcation position was not
influenced by oesophageal length in both cohorts (F(1,28)=2.49;
p=0.1257 and F(1,18)=1.92; p=0.183). Absolute carinal position
increased with oesophageal length, but relative position remained
constant at around 30% of proximal oesophageal length throughout
life.
Introduction
Experimental studies are often hampered by small sample sizes and low statistical power resulting in over-exaggerated effects and non-reproducibility of their results in humans (Ioannidis 2017). Basic research is however often the first step to advance understanding and therapy of human diseases. Levrat’s now iconic rat model of oesophageal adenocarcinoma (Levrat et al. 1962) offers the opportunity to conduct basic research into this carcinoma, whose pathophysiologic mechanisms may then be investigated in mice and thereafter tested in large animal models before transferal to patients (Kapoor et al. 2015). Critically, animal models should be designed to be as close as possible to the specific clinical situation they mimic (Festing and Altman 2002) (e.g., exploratory vs. confirmatory). In this respect, the relative position of the tracheal bifurcation to the oesophagus is of particular relevance in rat models of oesophageal atresia as this level typically determines fistula location (Diez-Pardo et al. 1996). In addition, this level also represents the preferred location for the high intrathoracic anastomosis following oesophagectomy (Yuan et al. 2015) which is used also in rat models (Man et al. 1988). This prompted us to investigate carinal position of the tracheal bifurcation relative to oesophageal length in order to contribute towards the design of reliable and translatable models of oesophageal diseases and surgery.
Materials and Methods
To reduce numbers of experimental animals used in research, data for this study were obtained from two cohorts of rats used in other studies. One study describes a linear relationship between bodyweight and oesophageal length and linear breaking strength in a cohort of 20 rats aged 15 to 444 days with two animals per investigated age (Oetzmann von Sochaczewskiet al.2019a). The other study investigated linear breaking strength of native oesophagi, those with a simple interrupted suture anastomosis, as well as oesophageal suture holding capacity in 30 rats at an age of eight weeks (Tagkalos et al. 2019).
All rats were outbred Sprague Dawley (RjHan:SD) of both sexes obtained
from Janvier Labs (Le Genest-Saint-Isle, France). They were housed in
our closed-facility under standard husbandry conditions in groups of
up to three animals per type-IV cage. The rats were provided with nest
material made of European aspen (Populus tremula) sized two
to three millimetres (Abbedd midi, Vienna, Austria), a tunnel and
environmental enrichments in the form of a red polycarbonate house and
four tissue papers of two gram each. Rats had access to sterilised
standard rat-chow (ssniff Ratte/Maus-Haltung Extrudat,
ssnif-Spezialdiäten, Soest, Germany) and water ad libitum. A
dark-light-cycle of 12 hours starting at 07:00 was employed in a room
with 67% relative humidity at 23°C and an air exchange of twelve times
per hour. Our experiments complied with the directive 2010/63/EU
(European Union 2010) and its subsequent national regulations for the
protection of animals. The German law for the protection of animals
exempts all experiments in which laboratory animals are sacrificed to
obtain isolated organs from approval by the competent state authority
(exact citation: section 7 subsection 2 sentence 3 of the German law
for the protection of animals [German citation: § 7 II 3
TierSchG]).
Rats were humanely killed by slowly increasing carbon dioxide
concentrations and had their oesophagus explanted, in a cluster of
viscera with the upper airways, using anatomical landmarks as
described elsewhere (Oetzmann von Sochaczewski et al. 2019b). The
oesophagus and upper airways were dissected free of surrounding
tissue, the carinal position of the tracheal bifurcation was then
marked on the oesophagus after which the airways were removed leaving
the oesophagus for length measurements using an electronic slide gauge
(VWR, Darmstadt, Germany) with a resolution of 0.01mm and an accuracy
of 0.03mm as depicted previously (Oetzmann von Sochaczewski et al.
2019c). The carinal position of the tracheal bifurcation was measured
from the proximal end of the oesophagus.
We used data obtained from exploratory investigations of five animals
per group to conduct a power analysis using G*Power (version 3.1.9.2)
(Faul et al. 2007) for a significant deviation of the regression
line’s slope from zero with a statistical power of 80% and an
alpha-level of five percent for the relationship between oesophageal
length and relative carinal position in both cohorts. In both cases, a
sample size of more than 10,000 oesophagi would be necessary to find a
significant deviation from zero, which indicates an extremely small
difference without biological relevance. Consequently, using the
previously described cohorts is suitable to describe the relationship
between oesophageal length and relative carinal position.
Correlation and regression analysis was conducted using R (version 3.5.1) with its stats4-package (R Core Team 2019). Normality of cohorts had been ensured using the Shapiro-Wilk-test (Oetzmann von Sochaczewski et al. 2019a; Tagkalos et al. 2019). To improve precision of our regression analysis, we conducted a bootstrap regression analysis using the simpleboot-package (version 1.1-7) (Peng 2019). In addition, we also bootstrapped a bias-corrected, accelerated (Efron 1987) 95% confidence interval of the mean relative carinal position using the boot-package (version 1.3-22) (Canty and Ripley 2019) and constructed bias-corrected, accelerated bootstrap 95% confidence intervals for correlation coefficients using the wBoot-package (version 1.0.3) (Weiss 2016). All bootstrap-procedures were based on 10,000 repetitions (Baumgart et al. 2020).
Results
Mean relative carinal position of the tracheal bifurcation, as measured from the proximal end of the oesophagus, was at 30.1% of oesophageal length (95% confidence interval: 29.6–31.5%) in rats aged eight weeks (n=30). In this cohort, oesophageal length and absolute carinal position were correlated with r=0.4 (95% confidence interval: 0.08–0.71; p=0.015) and it increased with oesophageal length (Figure 1A). As a result, the relative carinal position did not correlate with oesophageal length (r=-0.29, 95% confidence interval: -0.58–0.17; p=0.203) and did not change with increasing oesophageal length (Figure 1B).
Oesophageal length and absolute carinal position were highly
correlated in animals of different ages with r=0.92 (95%
confidence interval: 0.77–0.96; p=0.0066) and absolute
position also increased with oesophageal length (Figure 2A). Similar
to the other cohort, there was no correlation of oesophageal length
with relative carinal position (r=-0.31, 95% confidence
interval: -0.66–0.32; p=0.279), which also did not change
with increasing oesophageal length (Figure 2B).
Figure 1. Linear univariate regression of
oesophageal length for absolute and relative position of the
tracheal bifurcation in Click image to enlarge |
Figure 2. Linear univariate regression of
oesophageal length for absolute and relative position of the
tracheal bifurcation in
Click image to enlarge |
Discussion
The location of the tracheal bifurcation is of particular importance in oesophageal surgery: in neonates born with oesophageal atresia it often determines the location of trachea-oesophageal fistulas (Spitz, 2007)and in adults the anastomosis following oesophagectomy (Yuan et al. 2015). Incidentally, this is also the segment of the oesophagus with the lowest vascular and blood supply (Lister 1964; Oetzmann von Sochaczewski et al.; 2019d; Treutner et al. 1993). Fistula location and anastomotic site also play important roles in rat models of oesophageal diseases and surgery (Diez-Pardo et al. 1996; Man et al. 1988). As rats grow throughout their lives (Eisen 1976; Pahl 1969)we investigated whether airways would develop in a corresponding manner to keep a constant positon relative to the oesophagus or have a smaller growth rate resulting in a more cranial location of the tracheal bifurcation. Similarly, we analysed whether the carinal position would be relatively constant at the typical age of eight weeks of surgical models.
While Levrat’s initial experiments only lasted a month (Levrat
et al. 1962) it is now common to extend experiments to up to 80 weeks
(Gronnier et al. 2013). It therefore needs to be ensured that
anatomical positions remain comparable throughout study periods as
malignant trachea-oesophageal fistulae may develop. Their
investigation is of particular clinical interest because a malignant
trachea-oesophageal fistula shortens life expectations from months or
years to just weeks (Shamji and Inculet 2018). In contrast to
post-oesophagectomy trachea-oesophageal fistulae, which are inevitably
linked to anastomotic leaks (Lindner et al. 2017), not much is known
about their malignant counterparts (Shamji and Inculet 2018). A
similar relationship is present in oesophageal atresia: genetics and
associated anomalies have been investigated thoroughly (Bogset al.
2018; Zhang et al. 2017), but not much is known about recurrent
trachea-oesophageal fistulae and risk factors for their occurrence
(Smithers et al. 2017). This highlights the importance of relative
anatomical positions, in particular if these grave complications are
investigated in rats as the first choice model of basic research
(Kapooret al. 2015).
Our results demonstrate that the airways grow proportionally to the
oesophagus to maintain the relative position of the tracheal
bifurcation at the distal end of the proximal third of oesophageal
length. A word of caution is however necessary as our finding may not
be valid in all rat strains: it has previously been demonstrated that
Sprague Dawley rats have higher and organ weights than Fischer 344
rats (Schoeffner et al. 1999). Consequently, the relationship between
airways and oesophagus found in Sprague Dawley rats may not be the
same in other strains, particularly those with different growth
characteristics. In Sprague Dawley rats, proportional growth of
oesophagus and airways ensures reliability of the model in terms of
anatomical location for a variety of research topics ranging from
oesophageal atresia in the neonate to oesophageal malignancy in
geriatric patients.
Disclosure statement and funding details
This study was conducted without funding and we have nothing to
disclose.
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